A case of Blue rubber rleb nevus symdrome associated with intussusception.

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A case of Blue rubber bleb nevus symdrome was reported. A 22-year-old female was admitted to our hospital with complaints of abdominal pain and vomiting. There was no family history of the hemangioma and her parents were not consanguineous. She had the past history of the resection of cutaneous hemangioma several times. Emergency operation, performed on the second hospital day, revealing an acute intussusception of the small intestine, which was surgically removed. In the resected intestine, hemangioma of 12 X 10 X 8 mm in size was found, which was compatible with the tip of the intussusceptum. The same lesions were noticed in the remaining portion of small intestine and on the liver. Blue rubber bleb nevi were found also on the skin. Barium enema and endoscopic examination revealed the hemangioma at the descending colon. Histology of these hemangiomas showed a typical cavernous hemangioma. The cases of Blue rubber bleb nevus symdrome so far reported in Japan and abroad were reviewed.
社団法人日本消化器内視鏡学会の論文